Long-term follow-up of autologous hematopoietic stem cell transplantation for severe refractory Crohn's disease.

Daniel W Hommes, Marjolijn Duijvestein, Zuzana Zelinkova, Pieter C F Stokkers, Maartje Holsbergen-de Ley, Jaap Stoker, Carlijn Voermans, Marinus H J van Oers, Marie José Kersten
Author Information
  1. Daniel W Hommes: Department of Gastroenterology and Hepatology, Leiden University Medical Center, Leiden, the Netherlands. d.w.hommes@lumc.nl

Abstract

BACKGROUND: Although new therapeutic strategies have been developed to control Crohn's disease, medical treatment for refractory cases is not able to prevent extensive and/or repeat surgery. Recently, several cases have been reported of successful remission induction in Crohn's disease patients by means of hematopoietic stem cell transplantation (HSCT). Here we report our long-term (4 to 6 years) outcome in three patients.
patients: Three patients (two male, one female) with active severe Crohn's disease were planned to undergo autologous HSCT. All patients were intolerant or refractory to conventional therapies, including anti-TNFα antibodies. patients either refused surgery or surgery was considered not to be a feasible alternative due to the extensive disease involvement of the small intestine.
METHODS: Peripheral blood stem cells were mobilized using a single infusion of cyclophosphamide 4 g/m(2), followed on day 4 by subcutaneous injections with G-CSF 5 μg/kg twice daily until leukapheresis. CD34+ cells were isolated after leukapheresis by magnetic cell sorting. In two of the three patients a second round of stem cell mobilization using G-CSF only was required, either because of low yield or because of insufficient recovery after CD34 selection. Prior to transplantation, immune ablation was achieved using cyclophosphamide 50mg/kg/day (4 days), antithymocyte globulin 30 mg/kg/day (3 days) and prednisolone 500 mg (3 days). Endoscopy, barium small bowel enteroclysis and MRI enterography were performed.
RESULTS: All three patients successfully completed stem cell mobilization, and two of them subsequently underwent conditioning and autologous HSCT with CD34+ cell selection. Treatment was well tolerated, with acceptable toxicity. Now, 5 and 6 years post-transplantation, these patients are in remission under treatment. The third patient went into remission after mobilization and therefore she decided not to undergo conditioning and HSCT transplantation. After a successful pregnancy she relapsed two years later. Since then, she suffers from refractory Crohn's disease for which we are now reconsidering conditioning and transplantation.
CONCLUSION: Autologous HSCT appears to be safe and can be an alternative strategy for Crohn's disease patients with severe and therapy resistant disease.

MeSH Term

Adult
Crohn Disease
Female
Follow-Up Studies
Hematopoietic Stem Cell Mobilization
Hematopoietic Stem Cell Transplantation
Humans
Immunosuppressive Agents
Male
Middle Aged
Remission Induction
Transplantation Conditioning
Transplantation, Autologous
Treatment Outcome

Chemicals

Immunosuppressive Agents

Word Cloud

Created with Highcharts 10.0.0diseasepatientsCrohn'scellstemtransplantationHSCTrefractory4twosurgeryremissionyearsthreesevereautologoususingmobilizationdaysconditioningtreatmentcasesextensivesuccessfulhematopoietic6undergoeitheralternativesmallcellscyclophosphamideG-CSF5leukapheresisCD34+selection3BACKGROUND:Althoughnewtherapeuticstrategiesdevelopedcontrolmedicalablepreventand/orrepeatRecentlyseveralreportedinductionmeansreportlong-termoutcomePATIENTS:Threemaleonefemaleactiveplannedintolerantconventionaltherapiesincludinganti-TNFαantibodiesPatientsrefusedconsideredfeasibledueinvolvementintestineMETHODS:Peripheralbloodmobilizedsingleinfusiong/m2followeddaysubcutaneousinjectionsμg/kgtwicedailyisolatedmagneticsortingsecondroundrequiredlowyieldinsufficientrecoveryCD34Priorimmuneablationachieved50mg/kg/dayantithymocyteglobulin30mg/kg/dayprednisolone500mgEndoscopybariumbowelenteroclysisMRIenterographyperformedRESULTS:successfullycompletedsubsequentlyunderwentTreatmentwelltoleratedacceptabletoxicityNowpost-transplantationthirdpatientwentthereforedecidedpregnancyrelapsedlaterSincesuffersnowreconsideringCONCLUSION:AutologousappearssafecanstrategytherapyresistantLong-termfollow-up

Similar Articles

Cited By (16)